Research Topics
Genomes and Genes | Stephanie A HagstromSummaryAffiliation: Cleveland Clinic Foundation Country: USA Publications
Research Grants
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Detail Information
Publications
SOX2 mutation causes anophthalmia, hearing loss, and brain anomaliesStephanie A Hagstrom
Cole Eye Institute, Cleveland Clinic Foundation, Cleveland, Ohio 44195, USA
Am J Med Genet A 138:95-8. 2005....
Proteomic and genomic biomarkers for age-related macular degenerationJiayin Gu
Cole Eye Institute, Cleveland, OH, USA
Adv Exp Med Biol 664:411-7. 2010..CEP plasma biomarkers, particularly in combination with genomic markers, offer a potential early warning system for predicting susceptibility to this blinding disease...
Protective effect of paraoxonase 1 gene variant Gln192Arg in age-related macular degenerationGayle J T Pauer
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic, Cleveland, Ohio 44195, USA
Am J Ophthalmol 149:513-22. 2010..Paraoxonase 1 (PON1) protects against oxidative damage and has been evaluated for its involvement in aging diseases including AMD. This study investigated whether PON1 gene polymorphisms associate with AMD...
Mutation screen of beta-crystallin genes in 274 patients with age-related macular degenerationGwen M Sturgill
Louis Stokes Cleveland Department of Veterans Affairs Medical Center, Cleveland, Ohio, USA
Ophthalmic Genet 31:129-34. 2010..We therefore investigated CRYBB1 and CRYBB2 as candidate genes for AMD in 274 unrelated patients...
Early synaptic defects in tulp1-/- miceGregory H Grossman
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic, Cleveland, Ohio, USA
Invest Ophthalmol Vis Sci 50:3074-83. 2009..To investigate the role of Tulp1 in the photoreceptor synapse, the authors examined the presynaptic and postsynaptic architecture and retinal function in tulp1(-/-) mice..
Assessing susceptibility to age-related macular degeneration with proteomic and genomic biomarkersJiayin Gu
Cole Eye Institute, Lerner Research Inst, Cleveland Clinic Foundation, 9500 Euclid Ave, Cleveland, OH 44195, USA
Mol Cell Proteomics 8:1338-49. 2009..We conclude that CEP plasma biomarkers, particularly in combination with genomic markers, offer a potential early warning system for assessing susceptibility to this blinding, multifactorial disease...
Interaction between the photoreceptor-specific tubby-like protein 1 and the neuronal-specific GTPase dynamin-1Quansheng Xi
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic Foundation, Cleveland, Ohio 44195, USA
Invest Ophthalmol Vis Sci 48:2837-44. 2007..To investigate the function of TULP1 in maintaining the health of photoreceptors, the authors sought the identification of interacting proteins...
Tubby-like protein 1 (Tulp1) is required for normal photoreceptor synaptic developmentGregory H Grossman
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic, Cleveland, OH 44195, USA
Adv Exp Med Biol 664:89-96. 2010..Our new evidence indicates that Tulp1 is not only critical for photoreceptor function and survival, but is essential for the proper development of the photoreceptor synapse...
Mutation screen of the TUB gene in patients with retinitis pigmentosa and Leber congenital amaurosisQuansheng Xi
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic Foundation, 9500 Euclid Avenue, Cleveland, OH 44195, USA
Exp Eye Res 83:569-73. 2006..Although variant alleles of the TUB gene were found, none could be definitively associated with a specific retinal disease...
Sequence alterations in RX in patients with microphthalmia, anophthalmia, and colobomaNikolas J S London
Case Western Reserve University School of Medicine, Cleveland, OH, USA
Mol Vis 15:162-7. 2009..We screened a group of 24 patients with microphthalmia, coloboma, and/or anophthalmia for RX mutations...
Mutation screen of the cone-specific gene, CLUL1, in 376 patients with age-related macular degenerationGwen M Sturgill
Louis Stokes Cleveland Department of Veterans Affairs Medical Center, Cleveland, OH, USA
Ophthalmic Genet 27:151-5. 2006..Variant alleles of the CLUL1 gene were found; however, none are considered pathogenic. None of the variants identified are predicted to create or destroy splice donor or acceptor sites based on splice-site prediction software...
Immunocytochemical evidence of Tulp1-dependent outer segment protein transport pathways in photoreceptor cellsGregory H Grossman
Department of Ophthalmic Research, i31, Cole Eye Institute, Cleveland Clinic, 9500 Euclid Avenue, Cleveland, OH 44195, USA
Exp Eye Res 93:658-68. 2011..However, without Tulp1, two rhodopsin transport machinery proteins exhibit abnormal distribution, Rab8 and Rab11, suggesting a role for Tulp1 in vesicular docking and fusion at the plasma membrane near the connecting cilium...
Genetic analysis of complement factor H related 5, CFHR5, in patients with age-related macular degenerationUmadevi Narendra
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic Foundation, Cleveland, OH 44195, USA
Mol Vis 15:731-6. 2009..To investigate the complement factor H related 5 (CFHR5) gene, encoding a member of the complement factor H family, for the presence of genetic polymorphisms or mutations associated with age-related macular degeneration (AMD)...
Mutation screen of the membrane-type frizzled-related protein (MFRP) gene in patients with inherited retinal degenerationsGayle J T Pauer
Department of Ophthalmic Research, Cole Eye Institute, Cleveland Clinic Foundation, Cleveland, OH 44195, USA
Ophthalmic Genet 26:157-61. 2005..We identified five polymorphisms in the 5' untranslated region, four missense changes, six isocoding variants and four intronic changes. None of the sequence variants were interpreted as pathogenic...
Research Grants
- The Role of TULP1 in Photoreceptor CellsStephanie Hagstrom; Fiscal Year: 2007..It is possible that this work could form the foundation for future studies aimed at evaluating therapeutic modalities that might slow, stop, or reverse the course of retinal degeneration. ..
- The Role of TULP1 in Photoreceptor CellsStephanie Hagstrom; Fiscal Year: 2009..It is possible that this work could form the foundation for future studies aimed at evaluating therapeutic modalities that might slow, stop, or reverse the course of retinal degeneration. ..
