Research Topics
Genomes and Genes | Joseph J HigginsSummaryAffiliation: Center for Human Genetics and Child Neurology Country: USA Publications
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Detail Information
Publications
A mutation in a novel ATP-dependent Lon protease gene in a kindred with mild mental retardationJoseph J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, 279 Main St, Suite 203A, New Paltz, NY 12561, USA
Neurology 63:1927-31. 2004..Identifying the genetic factors that contribute to memory and learning is limited by the complexity of brain development and the lack of suitable human models for mild disorders of cognition...
An atypical intronic deletion widens the spectrum of mutations in hereditary spastic paraplegiaJ J Higgins
Laboratory of Neurogenetics, Wadsworth Center, New York State Department of Health, Albany, USA
Neurology 56:1482-5. 2001..To identify the genetic mutation responsible for autosomal dominant spastic paraplegia (HSP) in a large family with a "pure" form of the disorder...
HS1-BP3 gene variant is common in familial essential tremorJoseph J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, New Paltz, New York, USA
Mov Disord 21:306-9. 2006..The HS1-BP3 gene plays a putative role in regulating catecholamine and serotonin metabolism, but the functional consequences of the amino acid substitution (A265G) caused by this genetic variant is unknown...
A variant in the HS1-BP3 gene is associated with familial essential tremorJ J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, 279 Main St, Suite 203A, New Paltz, NY 12561, USA
Neurology 64:417-21. 2005..1 (ETM2). Linkage disequilibrium studies in separate population samples from the United States and Singapore suggest an association between ET and loci at ETM2...
Haplotype analysis at the ETM2 locus in a Singaporean sample with familial essential tremorJ J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, New Paltz, NY 12561, USA
Clin Genet 66:353-7. 2004..8% of elderly Singaporean controls (p = 0.0005). Haplotype studies in two different population samples suggest that a disease locus for ET lies near or within the 100-kb interval between the loci etm1231 and APOB...
Candidate genes for recessive non-syndromic mental retardation on chromosome 3p (MRT2A)J J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, 279 Main Street, New Paltz, NY 12561, USA
Clin Genet 65:496-500. 2004..The results suggest that a mutation does not exist in these genes and that an unknown transcript in the region contributes to the cognitive deficits in NSMR...
Integrated physical map of the human essential tremor gene region (ETM2) on chromosome 2p24.3-p24.2Joseph J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, New Paltz, New York 12561, USA
Am J Med Genet B Neuropsychiatr Genet 127:128-30. 2004..This physical map will provide a template for genomic sequencing and the identification of a gene for essential tremor...
Haplotype analysis of the ETM2 locus in familial essential tremorJoseph J Higgins
Center for Human Genetics and Child Neurology, Mid Hudson Family Health Institute, 279 Main Street, Suite 203A, New Paltz, NY 12561, USA
Neurogenetics 4:185-9. 2003..0063, n=35). This study provides evidence that an ancestral haplotype on chromosome 2p24.1 segregates with the ET disease phenotype in individuals with a family history of the disorder and will facilitate the search for a causative gene...
Dysregulation of large-conductance Ca2+-activated K+ channel expression in nonsyndromal mental retardation due to a cereblon p.R419X mutationJoseph J Higgins
Department of Pediatrics, Division of Pediatric Neurology, New York Presbyterian Hospital, Weill Cornell Medical College, New York, NY 10065, USA
Neurogenetics 9:219-23. 2008..Such alterations may contribute to cognitive impairments in patients with mild ARNSMR...
Temporal and spatial mouse brain expression of cereblon, an ionic channel regulator involved in human intelligenceJoseph J Higgins
Department of Pediatrics, Division of Pediatric Neurology, York Presbyterian Hospital, Weill Cornell Medical College, New York, New York 10065, USA
J Neurogenet 24:18-26. 2010..The results suggest that mutCRBN may cause ARNSID by disrupting the developmental regulation of BK(Ca) in brain regions that are critical for memory and learning...
Behavioral characterization of cereblon forebrain-specific conditional null mice: a model for human non-syndromic intellectual disabilityAnjali M Rajadhyaksha
Department of Pediatrics, Division of Pediatric Neurology, New York Presbyterian Hospital, Laboratory of Molecular and Developmental Neurobiology, Weill Cornell Medical College, 1300 York Avenue, New York, NY 10065, USA
Behav Brain Res 226:428-34. 2012....
Mutations in FLVCR1 cause posterior column ataxia and retinitis pigmentosaAnjali M Rajadhyaksha
Department of Pediatrics, New York Presbyterian Hospital, Weill Cornell Medical College, New York, 10065, USA
Am J Hum Genet 87:643-54. 2010..This finding broadens the molecular basis of sensory neural signaling to include common mechanisms that involve proprioception and vision...
A nonverbal learning disability in a case of central hypoventilation syndrome without a PHOX2B gene mutationRobert Trobliger
Neuropsychology, Northeast Regional Epilepsy Group, White Plains, New York, USA
Child Neuropsychol 16:202-8. 2010..Defining the psycho-educational needs in CCHS may avert compounding the emotional and medical stresses of this already debilitating disorder...
Hybridize and personalize: the new age of syndromal mental retardation diagnosticsMichael R Speicher
Neurology 68:721-2. 2007
X-linked oligophrenic vermian dysgenesis: syndromic vs non-syndromic X-linked mental retardation?Joseph J Higgins
Neurology 65:1346-7. 2005
