Research Topics
Species | K M D BushbySummaryAffiliation: University of Newcastle Country: UK Publications
| Collaborators
|
Detail Information
Publications
Report on the 124th ENMC International Workshop. Treatment of Duchenne muscular dystrophy; defining the gold standards of management in the use of corticosteroids. 2-4 April 2004, Naarden, The NetherlandsK Bushby
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE3 4YQ, UK
Neuromuscul Disord 14:526-34. 2004
Nonmolecular treatment for muscular dystrophiesKate Bushby
Newcastle upon Tyne Muscle Centre, Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne, UK
Curr Opin Neurol 18:511-8. 2005..This review highlights emerging evidence on the management of patients with muscular dystrophies...
107th ENMC international workshop: the management of cardiac involvement in muscular dystrophy and myotonic dystrophy. 7th-9th June 2002, Naarden, the NetherlandsK Bushby
Department of Neuromuscular Genetics, Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE1 3BZ, UK
Neuromuscul Disord 13:166-72. 2003
The 105th ENMC sponsored workshop: pathogenesis in the non-sarcoglycan limb-girdle muscular dystrophies, Naarden, April 12-14, 2002K M D Bushby
Institute of Human Genetics, International Centre for Life, Central Parkway, NE1 3BZ, Newcastle upon Tyne, UK
Neuromuscul Disord 13:80-90. 2003
Gene table: the limb-girdle muscular dystrophiesKate Buchby
Institute of Human Genetics, University of Newcastle upon Tyne, UK
Eur J Paediatr Neurol 6:233-4. 2002
145th ENMC International Workshop: planning for an International Trial of Steroid Dosage Regimes in DMD (FOR DMD), 22-24th October 2006, Naarden, The NetherlandsK Bushby
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE1 3BZ, UK
Neuromuscul Disord 17:423-8. 2007
Diagnosis and management of the limb girdle muscular dystrophiesKate Bushby
Pract Neurol 9:314-23. 2009..As more is understood about the clinical features of the different types of LGMD, targeted management is increasingly possible, especially focusing on those patients at high risk of cardiac and respiratory complications...
The limb-girdle muscular dystrophies-multiple genes, multiple mechanismsK M Bushby
Department of Human Genetics, Newcastle upon Tyne, UK
Hum Mol Genet 8:1875-82. 1999..At a practical level, despite the marked heterogeneity of this group real progress can at last be made in determining a precise diagnosis...
Making sense of the limb-girdle muscular dystrophiesK M Bushby
Department of Biochemistry and Genetics, University of Newcastle upon Tyne, UK
Brain 122:1403-20. 1999....
Muscle pain as a prominent feature of facioscapulohumeral muscular dystrophy (FSHD): four illustrative case reportsK M Bushby
Department of Human Genetics, Newcastle upon Tyne, UK
Neuromuscul Disord 8:574-9. 1998..We believe that pain in FSHD is an under-reported but significant symptom and that further work is necessary to determine its prevalence, understand its cause and provide effective treatment...
Interventions for muscular dystrophy: molecular medicines entering the clinicKate Bushby
Institute of Human Genetics, Newcastle University, Newcastle upon Tyne, UK
Lancet 374:1849-56. 2009..Various therapeutic targets are being investigated, from personalised medicines targeting specific mutations and drugs targeting cellular pathways to gene-based and cell-based therapies...
A founder mutation in Anoctamin 5 is a major cause of limb-girdle muscular dystrophyDebbie Hicks
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE1 3BZ, UK
Brain 134:171-82. 2011..191dupA, should be an early step in the diagnostic algorithm of adult limb-girdle muscular dystrophy patients...
Collagen VI related muscle disordersA K Lampe
Institute of Human Genetics, University of Newcastle upon Tyne, International Centre for Life, Central Parkway, Newcastle upon Tyne, NE1 3BZ
J Med Genet 42:673-85. 2005..Here we review the clinical phenotypes of BM and UCMD and their diagnosis and management, and provide an overview of the current knowledge of the pathogenesis of collagen VI related disorders...
Cyclosporine A treatment for Ullrich congenital muscular dystrophy: a cellular study of mitochondrial dysfunction and its rescueD Hicks
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne, UK
Brain 132:147-55. 2009..Further work is needed on the relationship of PTP dysregulation with UCMD pathology...
Automated genomic sequence analysis of the three collagen VI genes: applications to Ullrich congenital muscular dystrophy and Bethlem myopathyA K Lampe
Institute of Human Genetics, University of Newcastle upon Tyne, Newcastle upon Tyne, UK
J Med Genet 42:108-20. 2005..The large number of single nucleotide polymorphisms which we generated in the course of this work may be of importance in determining the major phenotypic variability seen in this group of disorders...
Multiplex SSCP and heteroduplex analysis with Southern hybridization for large-scale mutation detectionR Pogue
Department of Human Molecular Genetics, University of Newcastle upon Tyne, Ridley Building, Claremont Road, Newcastle upon Tyne, NE1 7RU, United Kingdom
Genomics 54:1-4. 1998..We confirmed the validity of our approach by detecting 90% of mutations in a blind study of previously characterized mutations in the adenomatous polyposis coli (APC) gene that underlies familial adenomatous polyposis...
Late onset in dysferlinopathy widens the clinical spectrumL Klinge
Institute of Human Genetics, University of Newcastle upon Tyne, International Centre for Life, Central Parkway, Newcastle upon Tyne, NE1 3BZ, United Kingdom
Neuromuscul Disord 18:288-90. 2008..This case represents the eldest age of onset of dysferlinopathy reported so far and widens the clinical spectrum of this disease...
Myoglobinuria in boys with Duchenne muscular dystrophy on corticosteroid therapyP Garrood
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE1 3BZ, UK
Neuromuscul Disord 18:71-3. 2008..Families and physicians need to have an increased awareness of this possibility and of the appropriate management of myoglobinuria...
Limb-girdle muscular dystrophies--from genetics to molecular pathologyS H Laval
Institute of Human Genetics, International Centre for Life, Newcastle-upon-Tyne, UK
Neuropathol Appl Neurobiol 30:91-105. 2004....
A gene related to Caenorhabditis elegans spermatogenesis factor fer-1 is mutated in limb-girdle muscular dystrophy type 2BR Bashir
Department of Human Genetics, University of Newcastle upon Tyne, United Kingdom
Nat Genet 20:37-42. 1998..The proposed name 'dysferlin' combines the role of the gene in producing muscular dystrophy with its C. elegans homology...
Characterisation of the dysferlin skeletal muscle promoterR M Foxton
Institute of Human Genetics, International Centre for Life, Central Parkway, Newcastle upon Tyne NE1 3BZ, UK
Eur J Hum Genet 12:127-31. 2004..Finally, the core promoter region has been screened for mutations in suspected dysferlinopathy patients...
The phenotype of limb-girdle muscular dystrophy type 2IM Poppe
Institute of Human Genetics, the University Newcastle upon Tyne, UK
Neurology 60:1246-51. 2003..CONCLUSIONS: LGMD2I due to FKRP mutations appears to be a relatively common cause of LGMD, with respiratory and cardiac failure as prominent complications...
Cloning of the mouse dysferlin gene and genomic characterization of the SJL-Dysf mutationE Vafiadaki
School of Biochemistry and Genetics, University of Newcastle upon Tyne, UK
Neuroreport 12:625-9. 2001..The identification of this mutation has implications for the various groups using this widely available mouse stock...
MRI for the demonstration of subclinical muscle involvement in muscular dystrophyS Sookhoo
Department of Neuroradiology, Newcastle upon Tyne, UK
Clin Radiol 62:160-5. 2007..To compare magnetic resonance imaging (MRI) with clinical examination for the detection of muscle abnormality in patients with muscular dystrophy...
The third human FER-1-like protein is highly similar to dysferlinS Britton
Molecular Genetics Unit, School of Biochemistry and Genetics, University of Newcastle upon Tyne, Newcastle upon Tyne, England, NE1 7RU, United Kingdom
Genomics 68:313-21. 2000..Sequence and predicted structural comparisons have highlighted the high degree of similarity of dysferlin and FER1L3, which have sequences corresponding to six C2 domains and which share more than 60% amino acid sequence identity...
EFNS guideline on diagnosis and management of limb girdle muscular dystrophiesF Norwood
Institute of Human Genetics, Newcastle upon Tyne, UK
Eur J Neurol 14:1305-12. 2007..The proposed guidelines suggest an approach to the diagnosis and monitoring of the limb girdle dystrophies in a manner accessible to general neurologists...
Steroid treatment causes deterioration of myocardial function in the {delta}-sarcoglycan-deficient mouse model for dilated cardiomyopathyR Bauer
Institute of Human Genetics, Newcastle University, International Center for Life, Newcastle upon Tyne NE1 3BZ, UK
Cardiovasc Res 79:652-61. 2008..The delta-sarcoglycan-deficient mouse (Sgcd-null) is a model for both limb girdle muscular dystrophy 2F (LGMD2F) and dilated cardiomyopathy...
A refined diagnostic algorithm for Bethlem myopathyD Hicks
Institute of Human Genetics, Newcastle University, Newcastle upon Tyne, NE1 3BZ, Great Britain
Neurology 70:1192-9. 2008..Unlike UCMD, BM is difficult to diagnose because of its clinical overlap with other contractural phenotypes and the lack of sensitivity of standard muscle biopsy immunohistochemical diagnostic techniques...
Diagnosis and management of Duchenne muscular dystrophy, part 1: diagnosis, and pharmacological and psychosocial managementKatharine Bushby
Institute of Human Genetics, Newcastle University, Newcastle upon Tyne, UK
Lancet Neurol 9:77-93. 2010..In part 1 of this Review, we describe the methods used to generate the recommendations, and the overall perspective on care, pharmacological treatment, and psychosocial management...
Exon skipping mutations in collagen VI are common and are predictive for severity and inheritanceA K Lampe
Division of Neurology, The Children s Hospital of Philadelphia and University of Pennsylvania School of Medicine, Philadelphia, Pennsylvania, USA
Hum Mutat 29:809-22. 2008....
