Research Topics
Species | B FowlerSummaryAffiliation: University of Basel Country: Switzerland Publications
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Detail Information
Publications
Quality of analytical performance in inherited metabolic disorders: the role of ERNDIMB Fowler
Metabolic Unit, University Children s Hospital, Roemergasse 8, Basel, 4058, Switzerland
J Inherit Metab Dis 31:680-9. 2008..There is considerable evidence that performance in biochemical genetic testing has improved since the introduction of ERNDIM schemes...
[Homocystein--an independent risk factor for cardiovascular and thrombotic diseases]B Fowler
Stoffwechselabteilung, Universitäts Kinderspital beider Basel, Basel
Ther Umsch 62:641-6. 2005..Elevated homocysteine can be lowered in such cases with a combination of folic acid, vitamin B12 vitamin B6. The results of ongoing trials on the impact of such treatment on risk of vascular disease are awaited with great interest...
The folate cycle and disease in humansB Fowler
Metabolic Unit, University Children s Hospital Basel UKBB, Basel, Switzerland
Kidney Int Suppl 78:S221-9. 2001..Knowledge of their catalytic and molecular properties is important in understanding possible causes of moderate hyperhomocysteinemia, as for example, the well-known 677 C-->T transition of methylene tetrahydrofolate reductase...
Causes of and diagnostic approach to methylmalonic aciduriasB Fowler
Metabolic Unit, University Children s Hospital, Roemergasse 8, Basel, CH 4058, Switzerland
J Inherit Metab Dis 31:350-60. 2008..The reliable characterization of patients with isolated MMAuria pinpoints the correct gene for mutation analysis. Reliable classification of these patients is essential for ongoing and future prospective studies on treatment and outcome...
Disturbed ratio of erythrocyte and plasma S-adenosylmethionine/S-adenosylhomocysteine in peripheral arterial occlusive diseaseF M Loehrer
Metabolic Unit, University Children's Hospital Basel, UKBB, Romergasse 8, CH-4005, Basel, Switzerland
Atherosclerosis 154:147-54. 2001..Since the ratio of AdoMet/AdoHcy is closely linked with the activity of numerous enzymatic methylation reactions, these results suggest that methylation may be impaired in these patients...
Effect of low doses of 5-methyltetrahydrofolate and folic acid on plasma homocysteine in healthy subjects with or without the 677C-->T polymorphism of methylenetetrahydrofolate reductaseP Litynski
University Children's Hospital, Basel, Switzerland
Eur J Clin Invest 32:662-8. 2002..A prolonged effect 6 months after ceasing treatment with 5-methyltetrahydrofolate in homozygous subjects represents a further phenotypic effect of the 677TT methylenetetrahydrofolate reductase genotype...
Five patients with a biotin-responsive defect in holocarboxylase formation: evaluation of responsiveness to biotin therapy in vivo and comparative biochemical studies in vitroT Suormala
Metabolic Unit, University Children s Hospital, Basel, Switzerland
Pediatr Res 41:666-73. 1997..The results in the five patients are in accordance with a primary defect of holocarboxylase synthetase due to a decreased affinity for biotin, in one patient combined with a decreased Vmax...
Mammalian TOR: a homeostatic ATP sensorP B Dennis
The Friedrich Miescher Institute for Biomedical Research, Maulbeerstrasse 66, CH 4058, Basel, Switzerland
Science 294:1102-5. 2001..Here we demonstrate that the mTOR pathway is influenced by the intracellular concentration of ATP, independent of the abundance of amino acids, and that mTOR itself is an ATP sensor...
Clinical use and rational management of homocysteine, folic acid, and B vitamins in cardiovascular and thrombotic diseasesO Stanger
Universitätsklinik für Herzchirurgie, Private Medizinische Universität, Landeskliniken Salzburg, Mullner Hauptstrasse 48, 5020 Salzburg, Austria
Z Kardiol 93:439-53. 2004..The results of ongoing randomized controlled intervention trials must be available before screening for and treatment of hyperhomocysteinemia can be recommended for the apparently healthy general population...
Intermediate hyperhomocysteinaemia and compound heterozygosity for the common variant c.677C>T and a MTHFR gene mutationT Rummel
Klinik und Poliklinik für Kinder und Jugendmedizin, Universitat Munster, Stoffwechsellabor, Munster, Germany
J Inherit Metab Dis 30:401. 2007..677TT genotype and might require in addition to folate substitution further therapy to normalize homocysteine levels...
Isolated 3-methylcrotonyl-coenzyme A carboxylase deficiency in a child with metabolic strokeL Pinto
, FFFCMPA, Brazil
J Inherit Metab Dis 29:205-6. 2006..We report a 3-year-old boy with isolated 3-methylcrotonyl-coenzyme A deficiency with unexpectedly severe presentation, seizures and history of cerebral ischae-mic episode...
Methionine adenosyltransferase (MAT) I/III deficiency with concurrent hyperhomocysteinaemia: two novel casesM Linnebank
Children s Hospital, University of Munster, Munster, Germany
J Inherit Metab Dis 28:1167-8. 2005..Thus, MAT I/III deficiency is important in the differential diagnoses of hyperhomocysteinaemia, which may lead to clinical complications of MAT I/III deficiency...
CblE type of homocystinuria due to methionine synthase reductase deficiency: clinical and molecular studies and prenatal diagnosis in two familiesP Zavadakova
Institute of Inherited Metabolic Diseases, Charles University, 1st Faculty of Medicine, Prague, Czech Republic
J Inherit Metab Dis 25:461-76. 2002..Our study expands the knowledge of the phenotypic and genotypic variability of the cblE type of homocystinuria and supports the concept that this disorder is caused by mutations in the MTRR gene...
3-OMD and homocysteine plasma levels in parkinsonian patientsTh Muller
Department of Neurology, St Josef Hospital, Ruhr University Bochum, Federal Republic of Germany
J Neural Transm 109:175-9. 2002..52, p = 0.0006) correlated to 3-OMD. Homocysteine induces vascular disease. Previous studies showed an increase of ischaemic heart- and cerebrovascular disease in treated parkinsonian patients...
Defects in human methionine synthase in cblG patientsS Gulati
Biochemistry Department, University of Nebraska, Lincoln 68588 0664, USA
Hum Mol Genet 5:1859-65. 1996..In addition, they suggest directly that mutations in methionine synthase can lead to elevated homocysteine, implicated both in neural tube defects and in cardiovascular diseases...
Renal heme metabolism in hereditary tyrosinemia: use of succinylacetone in rat renal tubulesP A Wyss
Department of Medicine, Medical College of Virginia, Richmond 23298
Biochim Biophys Acta 1070:300-4. 1991..Cytochrome P-450 content remained unaffected. Impairment of iron uptake and/or transport within the cell or enhancement of heme catabolism via a non-heme oxygenase-dependent pathway could explain the observations...
